Unravelling complex mosaicism of sex chromosomes in a patient with primary amenorrhea through cytogenetic analysis on urothelial cells


Por: Sevilla-Montoya, Rosalba, De Jesus Zavaleta-Abreu, Maria, Queipo, Gloria, SANCHEZ, SILVIA, FRIAS, SARA, Hidalgo-Bravo, Alberto, Grether-Gonzalez, Patricia

Publicada: 1 may 2021
Categoría: Obstetrics and gynecology

Resumen:
Objective: Sex chromosome mosaicism remains challenging in the study of disorders of sex development (DSD). Aneuploid cells in the developing gonad play a major role in sex determination. Therefore, it is necessary acknowledge their presence by different methods. Our aim was to stand out the utility of urothelial cells for unravelling complex and hidden cell lines in DSD patients. Case report: Herein we report on a 19-year-old female with primary amenorrhea, short stature without ambiguous external genitalia. She had a 45,X/46, XY karyotype in leukocytes. Interphase FISH revealed hidden 45,X/47,XYY/47,XXY/46,XY/46, XX mosaicism in leukocytes and urothelial cells. Conclusion: These findings highlight the importance of investigating sex chromosome mosaicism in other tissues. Of particular interest in cases of DSD are the cells from the urinary epithelium, which may reflect the cell composition of the urogenital ridge, the analysis of these cells should be considered within the clinical assessment of DSD patients. (c) 2021 Taiwan Association of Obstetrics & Gynecology. Publishing services by Elsevier B.V. This is an open access article under the CC BY-NC-ND license (http://creativecommons.org/licenses/by-nc-nd/4.0/).

Filiaciones:
Sevilla-Montoya, Rosalba:
 Natl Inst Perinatol, Dept Genet & Human Genom, Montes Urales 800,Lomas Chapultepec IV Secc, Mexico City 11000, DF, Mexico

De Jesus Zavaleta-Abreu, Maria:
 Natl Inst Perinatol, Dept Genet & Human Genom, Montes Urales 800,Lomas Chapultepec IV Secc, Mexico City 11000, DF, Mexico

Queipo, Gloria:
 Univ Nacl Autonoma Mexico, Human Genet Dept, Gen Hosp Mexico, Sch Med, Dr Balmis 148, Mexico City 06720, DF, Mexico

SANCHEZ, SILVIA:
 Natl Inst Pediat, Cytogenet Lab, Insurgentes Sur 3700, Mexico City 04530, DF, Mexico

FRIAS, SARA:
 Natl Inst Pediat, Cytogenet Lab, Insurgentes Sur 3700, Mexico City 04530, DF, Mexico

 Univ Nacl Autonoma Mexico, Biomed Res Inst, Mexico City 04510, DF, Mexico

Hidalgo-Bravo, Alberto:
 Natl Inst Rehabil, Dept Genet, Calzada Mexico Xochimilco 289, Mexico City 14389, DF, Mexico

Grether-Gonzalez, Patricia:
 Natl Inst Perinatol, Dept Genet & Human Genom, Montes Urales 800,Lomas Chapultepec IV Secc, Mexico City 11000, DF, Mexico

 ABC Med Ctr, Av Carlos Fernandez Graef 154, Mexico City 05330, DF, Mexico
ISSN: 10284559
Editorial
Elsevier Ltd, RM N-412, 4F, CHIA HSIN BUILDING 11, NO 96, ZHONG SHAN N ROAD SEC 2, TAIPEI, 10449, TAIWAN, Taiwan
Tipo de documento: Article
Volumen: 60 Número: 3
Páginas: 526-529
WOS Id: 000651121800025
ID de PubMed: 33966741
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