Cutaneous mastocytosis in children: A children analysis of 71 cases


Por: Kiszewski A.E., Durán-McKinster C., Orozco-Covarrubias L., Gutiérrez-Castrellón P., Ruiz-Maldonado R.

Publicada: 1 ene 2004
Resumen:
Objective. To characterized the clinical features the clinical features, response to therapy, evolution and prognosis of cutaneous mastocytosis in children. Background. Mastocytosis in children, instead of being induced by a potentially oncogenic c-kit mutation is probably a clonal disease with benign prognosis. Methods. The clinicopathological features, evolution and response to treatment were analysed in 71 children with mastocytosis. Results. There were 53 (75%) cases of urticaria pigmentosa, 12 (17%) cases of mastocytoma, and six (8%) cases of diffuse cutaneous mastocytosis. In 92% of cases disease onset was in the first year of life. There was a male predominance 1.8: 1. Treatment did not modify the disease evolution. Eighty per cent of patients improved or had spontaneous resolution of the disease. Conclusion. The most frequent clinical form of mastocytosis was urticaria pigmentosa followed by mastocytoma and diffuse cutaneous mastocytosis. Darier's sign was present in 94% of cases. A negative Darier's sign does not rule out mastocytosis. In contrast to adults, mastocytosis in children usually has a benign course making sophisticated or invasive diagnostic tests unnecessary. A classification of paediatric cutaneous mastocytosis is proposed. © 2004 European Academy of Dermatology and Venereology.

Filiaciones:
Kiszewski A.E.:
 Department of Dermatology, National Institute of Paediatrics, Insurgentes Sur 3700-C, Mexico DF, 04530, Mexico

Durán-McKinster C.:
 Department of Dermatology, National Institute of Paediatrics, Insurgentes Sur 3700-C, Mexico DF, 04530, Mexico

Orozco-Covarrubias L.:
 Department of Dermatology, National Institute of Paediatrics, Insurgentes Sur 3700-C, Mexico DF, 04530, Mexico

Gutiérrez-Castrellón P.:
 Department of Clinical Research, National Institute of Paediatrics, Insurgentes Sur 3700-C, Mexico DF, 04530, Mexico

Ruiz-Maldonado R.:
 Department of Dermatology, National Institute of Paediatrics, Insurgentes Sur 3700-C, Mexico DF, 04530, Mexico
ISSN: 09269959
Editorial
WILEY-BLACKWELL PUBLISHING, INC, COMMERCE PLACE, 350 MAIN ST, MALDEN 02148, MA USA, Estados Unidos America
Tipo de documento: Article
Volumen: 18 Número: 3
Páginas: 285-290
WOS Id: 000221224700011
ID de PubMed: 15096137