Crystal structure of human cystatin C stabilized against amyloid formation


Por: Kolodziejczyk R., Michalska K., Hernandez-Santoyo A., Wahlbom M., Grubb A., Jaskolski M.

Publicada: 1 abr 2010
Resumen:
Human cystatin C (HCC) is a family 2 cystatin inhibitor of papain-like (C1) and legumain-related (C13) cysteine proteases. In pathophysiological processes, the nature of which is not understood, HCC is codeposited in the amyloid plaques of Alzheimer's disease or Down's syndrome. The amyloidogenic properties of HCC are greatly increased in a naturally occurring L68Q variant, resulting in fatal cerebral amyloid angiopathy in early adult life. In all crystal structures of cystatin C studied to date, the protein has been found to form 3D domain-swapped dimers, created through a conformational change of a beta-hairpin loop, L1, from the papain-binding epitope. We have created monomer-stabilized human cystatin C, with an engineered disulfide bond (L47C)-(G69C) between the structural elements that become separated upon domain swapping. The mutant has drastically reduced dimerization and fibril formation properties, but its inhibition of papain is unaltered. The structure confirms the success

Filiaciones:
Kolodziejczyk R.:
 Faculty of Chemistry, Department of Crystallography, A. Mickiewicz University, Grunwaldzka 6, 60-780 Poznan, Poland

Michalska K.:
 Faculty of Chemistry, Department of Crystallography, A. Mickiewicz University, Grunwaldzka 6, 60-780 Poznan, Poland

Hernandez-Santoyo A.:
 Univ Nacl Autonoma Mexico, Inst Quim, Mexico City 04510, DF, Mexico

Wahlbom M.:
 Department of Clinical Chemistry, Lund University, Sweden

Grubb A.:
 Department of Clinical Chemistry, Lund University, Sweden

Jaskolski M.:
 Faculty of Chemistry, Department of Crystallography, A. Mickiewicz University, Grunwaldzka 6, 60-780 Poznan, Poland

 Center for Biocrystallographic Research, Institute of Bioorganic Chemistry, Polish Academy of Sciences, Poznan, Poland
ISSN: 1742464X
Editorial
WILEY-BLACKWELL PUBLISHING, INC, COMMERCE PLACE, 350 MAIN ST, MALDEN 02148, MA USA, Estados Unidos America
Tipo de documento: Article
Volumen: 277 Número: 7
Páginas: 1726-1737
WOS Id: 000275634500012
ID de PubMed: 20175878
imagen Bronze